DOI: 10.1097/ipc.0000000000001668 ISSN: 1536-9943
CARD9 Deficiency Mimicking Hyper-IgE Syndrome
Merve Kiliç Çil, Ümmühan Çay, Özlem Özgür Gündeşlioğlu, Derya Alabaz, Derya Ufuk Altintaş
Caspase recruitment domain-containing protein 9 (CARD9) deficiency is a rare primary immunodeficiency characterized by a profound susceptibility to invasive fungal infections. Given its significant phenotypic overlap with hyper-IgE syndrome (HIES)—most notably, markedly elevated serum IgE levels—misdiagnosis remains a perilous clinical pitfall. We present 2 siblings from a consanguineous family harboring a rare homozygous nonsense mutation (
c.32G>A, p.Trp11*
) in the CARD9 gene, both presenting with severe invasive candidiasis. Case 1 developed vertebral osteomyelitis and central nervous system abscesses, while case 2 presented with fungal arthritis. Alarmingly, case 2 was misdiagnosed with juvenile idiopathic arthritis and erroneously treated with potent immunosuppressants, risking a catastrophic exacerbation of the fungal pathology. Following molecular confirmation, both were scheduled for curative hematopoietic stem cell transplantation. This report underscores the imperative of considering CARD9 deficiency in HIES-like presentations to avert detrimental immunosuppressive interventions.