DOI: 10.1111/ncn3.12824 ISSN: 2049-4173

A patient presenting downbeat positioning nystagmus with 19/11 CAG repeats in the CACNA1A gene: A case report

Hiroaki Yaguchi, Megumi Abe, Keishi Fujiwara, Akihiko Kudo, Ryoji Naganuma, Hisashi Uwatoko, Shinichi Shirai, Ikuko Takahashi‐Iwata, Masaaki Matsushima, Ichiro Yabe

Abstract

Spinocerebellar ataxia type 6 (SCA6) is a polyglutamine disorder caused by the expansion of CAG repeats in the gene encoding voltage‐gated calcium channel subunit alpha1 A (CACNA1A). The clinical features of SCA6 include slowly progressive cerebellar ataxia and downbeat positioning nystagmus. The clinical significance of 19 CAG repeats is unclear. We report a case with 19/11 CAG repeats in CACNA1A determined by direct sequencing. The case presented with DPN, which is one of the most important symptoms of SCA6, but did not present with ataxia.

More from our Archive